Journal of the American Society of Echocardiography
Volume 23, Issue 8 , Pages 848-853, August 2010

Exercise-Induced Left Ventricular Systolic Dysfunction in Women Heterozygous for Dystrophinopathy

  • Robert M. Weiss, MD

      Affiliations

    • Division of Cardiovascular Medicine, University of Iowa, Iowa City, Iowa
    • Corresponding Author InformationReprint requests: Robert M. Weiss, MD, University of Iowa Hospitals and Clinics, Division of Cardiovascular Medicine, Department of Internal Medicine, 200 Hawkins Drive, Room E317-1 GH, Iowa City, IA 52242.
  • ,
  • Richard E. Kerber, MD, FASE

      Affiliations

    • Division of Cardiovascular Medicine, University of Iowa, Iowa City, Iowa
  • ,
  • Jane K. Jones, RDCS, FASE

      Affiliations

    • Division of Cardiovascular Medicine, University of Iowa, Iowa City, Iowa
  • ,
  • Carrie M. Stephan, BSN, MA

      Affiliations

    • Department of Pediatrics, University of Iowa, Iowa City, Iowa
  • ,
  • Christina J. Trout, MSN

      Affiliations

    • Department of Pediatrics, University of Iowa, Iowa City, Iowa
  • ,
  • Paul D. Lindower, MD, FASE

      Affiliations

    • Division of Cardiovascular Medicine, University of Iowa, Iowa City, Iowa
  • ,
  • Kimberly S. Staffey, MD

      Affiliations

    • Division of Cardiovascular Medicine, University of Iowa, Iowa City, Iowa
  • ,
  • Kevin P. Campbell, PhD

      Affiliations

    • Division of Cardiovascular Medicine, University of Iowa, Iowa City, Iowa
    • Department of Neurology, University of Iowa, Iowa City, Iowa
    • Department of Molecular Physiology and Biophysics, University of Iowa, Iowa City, Iowa
    • Carver College of Medicine, and the Howard Hughes Medical Institute, University of Iowa, Iowa City, Iowa
  • ,
  • Katherine D. Mathews, MD

      Affiliations

    • Department of Pediatrics, University of Iowa, Iowa City, Iowa

published online 21 June 2010.

Background

Mutations in the X-linked gene encoding dystrophin cause skeletal and cardiac muscle diseases in men. Female “carriers” also can develop overt disease. The purpose of this study was to ascertain the prevalence of cardiac contractile abnormalities in dystrophinopathy carriers.

Methods

Twenty-four dystrophinopathy heterozygotes and 24 normal women each underwent standard exercise stress echocardiography.

Results

Heterozygotes demonstrated mildly lower left ventricular ejection fractions (LVEFs) at rest compared with controls (0.56 ± 0.10 vs 0.62 ± 0.07, P = .02). After exercise, the mean LVEF fell to 0.53 ± 0.14 in heterozygotes but rose to 0.73 ± 0.07 in controls (P < .001). Twenty-one of 24 dystrophinopathy heterozygotes demonstrated ≥1 of the following: abnormal resting LVEF, abnormal LVEF response to exercise, or exercise-induced wall motion abnormality.

Conclusions

Women heterozygous for dystrophinopathy demonstrate significant left ventricular systolic dysfunction, which is unmasked by exercise. This finding has mechanistic implications for both inherited and acquired cardiac disease states.

Keywords: Cardiomyopathy, Women, Exercise, Heart failure, Echocardiography

Abbreviation: LVEF, Left ventricular ejection fraction

To access this article, please choose from the options below

Login to an existing account or Register a new account.

  • Purchase this article for 31.50 USD (You must login/register to purchase this article)

    Online access for 24 hours. The PDF version can be downloaded as your permanent record.

  • Subscribe to this title

    Get unlimited online access to this article and all other articles in this title 24/7 for one year.

  • Claim access now

    For current subscribers with Society Membership or Account Number.

  • Visit SciVerse ScienceDirect to see if you have access via your institution.
 

 This work was supported by a research grant from the Muscular Dystrophy Association (Tucson, AZ) and by a Paul D. Wellstone Muscular Dystrophy Cooperative Research Center Grant from the National Institutes of Health (Bethesda, MD). Dr Campbell is an investigator of the Howard Hughes Medical Institute (Chevy Chase, MD).

PII: S0894-7317(10)00419-0

doi:10.1016/j.echo.2010.05.007

Journal of the American Society of Echocardiography
Volume 23, Issue 8 , Pages 848-853, August 2010